Int J Surg Case Rep. 2017;34:110-114. doi: 10.1016/j.ijscr.2017.03.028. Epub 2017 Mar 21.
From tooth extraction to Gorham-Stout disease: A case report.
International journal of surgery case reports
Gabriele Bocchialini, Luca Ferrari, Dante Burlini
Affiliations
Affiliations
- Maxillofacial Pediatric Surgery Unit, Ospedale dei Bambini-Asst., Spedali Civili, Brescia, Italy. Electronic address: [email protected].
- Maxillofacial Pediatric Surgery Unit, Ospedale dei Bambini-Asst., Spedali Civili, Brescia, Italy.
PMID: 28384557
PMCID: PMC5382024 DOI: 10.1016/j.ijscr.2017.03.028
Abstract
INTRODUCTION: Gorham-Stout disease (GSD), or vanishing bone disease, is a very rare condition of unknown aetiology. It is characterised by progressive osteolysis and angiomatosis.
CASE PRESENTATION: We report the discovery of this very rare disease following a trivial deciduous tooth extraction in a 14-year-old female. We focus initially on the difference between the preoperative orthopantomography and the whole-body computed tomography and magnetic resonance images obtained post-haemorrhage, and then on the improvement of strategies for the correct diagnosis and treatment of this disease.
DISCUSSION: Bone loss and the proliferation of vascular structures can occur in a single bone or spread to soft tissue and adjacent bone; areas commonly affected by GSD include the ribs, spine, pelvis, skull, clavicle, and the maxillofacial area. The clinical presentation of GSD includes pain, functional impairment, and swelling, although a few asymptomatic cases have been reported, similar to our case.
CONCLUSION: We report a very rare case of this multicentric disease in an asymptomatic child who presented for dental extraction, almost died, and was then diagnosed with and treated for GSD.
Copyright © 2017 The Authors. Published by Elsevier Ltd.. All rights reserved.
Keywords: Case report; Gorham-Stout disease; Haemorrhage; Oral surgery
References
- J Bone Joint Surg Am. 1977 Jan;59(1):57-61 - PubMed
- J Oral Maxillofac Surg. 2003 Aug;61(8):957-63 - PubMed
- Int J Surg. 2016 Oct;34:180-186 - PubMed
- J Pediatr Orthop. 1989 Sep-Oct;9(5):604-8 - PubMed
- Clin Orthop Relat Res. 1998 Feb;(347):268-71, 287-90 - PubMed
- World J Orthop. 2014 Nov 18;5(5):694-8 - PubMed
- J Pediatr Orthop. 1987 Jan-Feb;7(1):96-9 - PubMed
- J Pathol. 2001 Dec;195(5):624-30 - PubMed
- Int Orthop. 1990;14(4):361-6 - PubMed
- Arch Orthop Trauma Surg. 1995;114(4):207-10 - PubMed
- J Comput Assist Tomogr. 1994 Nov-Dec;18(6):985-9 - PubMed
- Schweiz Med Wochenschr. 1989 May 20;119(20):671-7 - PubMed
- AJR Am J Roentgenol. 1990 Jun;154(6):1335-6 - PubMed
- J Oral Maxillofac Surg. 2008 May;66(5):1073-6 - PubMed
- Rofo. 1991 Dec;155(6):579-81 - PubMed
- J Pediatr. 1969 Aug;75(2):243-52 - PubMed
- Clin Orthop Relat Res. 1974;(103):206-11 - PubMed
- J Bone Joint Surg Am. 1977 Apr;59(3):405-6 - PubMed
- Clin Rheumatol. 2016 Mar;35(3):813-23 - PubMed
- Korean J Radiol. 2013 Nov-Dec;14(6):946-50 - PubMed
- Skeletal Radiol. 1993 Aug;22(6):464-7 - PubMed
- Oral Surg Oral Med Oral Pathol. 1990 Dec;70(6):698-703 - PubMed
- Clin Radiol. 2012 Aug;67(8):782-8 - PubMed
- Chest. 1987 Jul;92(1):189 - PubMed
- Clin Rheumatol. 2005 Sep;24(5):551-5 - PubMed
- J Can Assoc Radiol. 1973 Jun;24(2):98-103 - PubMed
- Skeletal Radiol. 2013 Jul;42(7):917-24 - PubMed
- J Bone Joint Surg Br. 1985 Jan;67(1):88-93 - PubMed
- Int J Surg Case Rep. 2017;31:237-240 - PubMed
- J Bone Joint Surg Am. 1955 Oct;37-A(5):985-1004 - PubMed
- Rheumatology (Oxford). 1999 Sep;38(9):904-5 - PubMed
- Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 2010 Feb;109(2):e41-8 - PubMed
- J Zhejiang Univ Sci B. 2013 Aug;14(8):729-35 - PubMed
- Metab Bone Dis Relat Res. 1983-1984;5(2):53-60 - PubMed
- Anaesthesia. 2000 Feb;55(2):157-9 - PubMed
- Oral Surg Oral Med Oral Pathol. 1983 Apr;55(4):331-43 - PubMed
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