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Zargari O, Asadi M, Azimi SZ, et al. Rhabdomyomatous mesenchymal hamartoma presenting as telangiectasia in a 57-year-old man. J Cutan Pathol. 2021;48(9):1182-1184doi: 10.1111/cup.14044.
Zargari, O., Asadi, M., Azimi, S. Z., & Mesbah, A. (2021). Rhabdomyomatous mesenchymal hamartoma presenting as telangiectasia in a 57-year-old man. Journal of cutaneous pathology, 48(9), 1182-1184. https://doi.org/10.1111/cup.14044
Zargari, Omid, et al. "Rhabdomyomatous mesenchymal hamartoma presenting as telangiectasia in a 57-year-old man." Journal of cutaneous pathology vol. 48,9 (2021): 1182-1184. doi: https://doi.org/10.1111/cup.14044
Zargari O, Asadi M, Azimi SZ, Mesbah A. Rhabdomyomatous mesenchymal hamartoma presenting as telangiectasia in a 57-year-old man. J Cutan Pathol. 2021 Sep;48(9):1182-1184. doi: 10.1111/cup.14044. Epub 2021 Jun 04. PMID: 33964023.
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J Cutan Pathol. 2021 Sep;48(9):1182-1184. doi: 10.1111/cup.14044. Epub 2021 Jun 04.

Rhabdomyomatous mesenchymal hamartoma presenting as telangiectasia in a 57-year-old man.

Journal of cutaneous pathology

Omid Zargari, Masih Asadi, Seyyede Zeinab Azimi, Alireza Mesbah

Affiliations

  1. Skin Research Center, Shahid Beheshti University of Medical Sciences, Tehran, Iran.
  2. York University, Toronto, Canada.
  3. Center for Research & Training in Skin Diseases & Leprosy, Tehran University of Medical Sciences, Tehran, Iran.
  4. Razi Laboratory, Rasht, Iran.

PMID: 33964023 DOI: 10.1111/cup.14044

Abstract

Rhabdomyomatous mesenchymal hamartoma (RMH) is a rare congenital malformation of the dermis and subcutaneous tissue. Usually, RMH occurs in the midline of the face and neck region. We described a case of RMH presenting as telangiectasia in a 57-year-old man with a history of pityriasis lichenoides chronicus. Histopathological examination revealed a subepidermal haphazard proliferation of striated muscular tissue perpendicular to the epidermis. These bundles of striated muscular tissue were admixed with adnexal structures. The diagnosis was consistent with RMH. RMH is more common in the neonatal period or in young children, but we should consider it as part of a differential diagnosis in older adults as well.

© 2021 John Wiley & Sons A/S. Published by John Wiley & Sons Ltd.

Keywords: hamartoma; mesenchymal; rhabdomyomatous; soft tissue neoplasms

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